CPC C12N 15/113 (2013.01) [A61K 31/7125 (2013.01); A61K 47/6807 (2017.08); A61K 47/6849 (2017.08); A61K 47/6889 (2017.08); A61K 48/005 (2013.01); A61P 21/00 (2018.01); A61P 21/06 (2018.01); C07K 16/2881 (2013.01); C07K 19/00 (2013.01); C07K 2317/55 (2013.01); C12N 2310/11 (2013.01); C12N 2310/14 (2013.01); C12N 2310/31 (2013.01); C12N 2310/313 (2013.01); C12N 2310/321 (2013.01); C12N 2310/3231 (2013.01); C12N 2310/3513 (2013.01); C12N 2320/32 (2013.01)] | 16 Claims |
1. A method of delivering an oligonucleotide to a subject, wherein the subject has facioscapulohumeral muscular dystrophy (FSHD), the method comprising intravenously administering to the subject a conjugate that comprises an anti-transferrin receptor antibody covalently linked to a 5′ end or a 3′ end of an oligonucleotide, wherein the oligonucleotide comprises one or more modifications and a strand that comprises a region of complementarity of at least 15 nucleotides in length to the nucleotide sequence of DUX4 mRNA;
wherein the oligonucleotide is in the range of 15-35 nucleotides in length; wherein the one or more modifications comprise a 2′-modified nucleoside selected from the group consisting of a 2′-O-methyl nucleoside, a 2′-fluoro nucleoside, a 2′-O-methoxyethyl nucleoside, and 2′,4′-bridged nucleosides, and combinations thereof, and/or comprise a modified backbone selected from a backbone comprising one or more phosphorothioate linkages and a phosphorodiamidate morpholino backbone; and
wherein the oligonucleotide brings about degradation of DUX4 mRNA as measured by the decreased expression of DUX4 biomarker RNAs comprising ZSCAN4 and LEUTX in the muscle cell.
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